Abstract
Background
Penile agenesis occurs in 1 in 30 million births. The cause of this anomaly is the failure of development of genital tubercle. Case Report: A 1-day-old neonate was born with complete penile agenesis. Imaging investigations showed an ectopic urethral insertion in the anterior wall of the rectum, and a grade 3 left vesicoureteral reflux. Conclusion: Penile agenesis is a complex genital abnormality. It can be associated with urinary malformations that should be systematically investigated.